TY - JOUR
T1 - Adult intestinal malrotation presenting as caecal volvulus with incidental findings of duplicate inferior vena cava and other rare abnormalities
T2 - case report
AU - Thomson, Samuel R.
AU - Hanna, Sam M.
AU - Sarkar, Amit
AU - Das, Atandrila
AU - Perera, Dayashan S.
N1 - Publisher Copyright:
© The Author(s) 2024.
PY - 2024/3/1
Y1 - 2024/3/1
N2 - Intestinal malrotation and duplication of the inferior vena cava are rarely diagnosed in adult patients; however, incidence is likely underestimated as they are usually asymptomatic. These congenital malformations have been previously reported in the same patient twice but never with colonic obstruction or ischaemia. A 25-year-old female presented with nausea, vomiting, obstipation, and abdominal pain, and on computed tomography of the abdomen and pelvis was diagnosed with a caecal volvulus and pneumatosis coli associatedwithintestinalmalrotationrequiringemergencyrighthemicolectomy.Incidentally,thepatientwasnotedtohaveduplication of the inferior vena cava, azygos continuation of the inferior vena cava, and splenic fragmentation. This constellation of symptoms has not been reported in the literature previously. The pattern of malformations follows that of polysplenia syndrome. Although rare, awareness of these malformations can be useful to clinicians.
AB - Intestinal malrotation and duplication of the inferior vena cava are rarely diagnosed in adult patients; however, incidence is likely underestimated as they are usually asymptomatic. These congenital malformations have been previously reported in the same patient twice but never with colonic obstruction or ischaemia. A 25-year-old female presented with nausea, vomiting, obstipation, and abdominal pain, and on computed tomography of the abdomen and pelvis was diagnosed with a caecal volvulus and pneumatosis coli associatedwithintestinalmalrotationrequiringemergencyrighthemicolectomy.Incidentally,thepatientwasnotedtohaveduplication of the inferior vena cava, azygos continuation of the inferior vena cava, and splenic fragmentation. This constellation of symptoms has not been reported in the literature previously. The pattern of malformations follows that of polysplenia syndrome. Although rare, awareness of these malformations can be useful to clinicians.
KW - caecal volvulus
KW - duplicate inferior vena cava
KW - intestinal malrotation
KW - polysplenia syndrome
UR - http://www.scopus.com/inward/record.url?scp=85187667449&partnerID=8YFLogxK
U2 - 10.1093/jscr/rjae132
DO - 10.1093/jscr/rjae132
M3 - Article
AN - SCOPUS:85187667449
SN - 2042-8812
VL - 2024
JO - Journal of Surgical Case Reports
JF - Journal of Surgical Case Reports
IS - 3
M1 - rjae132
ER -